KCNQ1 Variant R360M

Summary of observed carriers, functional annotations, and structural context for KCNQ1 R360M. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT1 penetrance

79%

10/13 effective observations

Total carriers

3

3 LQT1 · 0 unaffected

Functional studies

0

Publications with functional data

R360M has not been reported in gnomAD. This residue resides in a Hotspot region for LQT1.

Variant features alone are equivalent to phenotyping 7 individuals with LQT1 and 3 unaffected individuals.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density LQT1 (%)
-5.61 0.999 0 0.934 82

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. BLAST-PSSM reflects evolutionary conservation; more negative values indicate rarer substitutions. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT1 Other Disease
21956039 2011 1 None 1 None
19716085 2009 2 None 2 None
Literature, cohort, and gnomAD 3 0 3
Variant features alone 15 3 7

Totals may differ from individual publications due to duplicate patients removed during curation.

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near R360M.
Neighbour residue Distance (Å) Observed variants
538 11
537 11
539 12 R539W, R539L, R539Q
531 13
360 13 R360ins, R360G, R360M,
357 14 Q357H, Q357H,
536 14
353 14 L353P,
356 14
535 14
541 15 V541I,
540 15
534 15
532 15