KCNQ1 Variant G325W

Summary of observed carriers, functional annotations, and structural context for KCNQ1 G325W. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT1 penetrance

80%

8/11 effective observations

Total carriers

1

1 LQT1 · 0 unaffected

Functional studies

0

Publications with functional data

G325W has not been reported in gnomAD. This residue resides in a Hotspot region for LQT1.

Variant features alone are equivalent to phenotyping 7 individuals with LQT1 and 3 unaffected individuals.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density LQT1 (%)
-7.58 1.0 -4 0.974 88

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. BLAST-PSSM reflects evolutionary conservation; more negative values indicate rarer substitutions. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT1 Other Disease
32893267 2020 1 None 1 None
Literature, cohort, and gnomAD 1 0 1
Variant features alone 15 3 7

Totals may differ from individual publications due to duplicate patients removed during curation.

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near G325W.
Neighbour residue Distance (Å) Observed variants
325 0 G325R, G325R, G325E, G325W,
324 4
328 4 I328del,
322 5 T322M, T322A, T322K,
327 5 T327A, T327S, T327S,
320 6 P320H, P320A, P320S,
329 6 A329T,
283 6 A283G, A283T,
284 7 E284K,
323 7
321 8
330 8
279 8 F279I,
282 9 L282P,
331 9
332 10
287 11 A287E, A287T, A287S,
333 11
278 11 Y278H,
304 11 W304R, W304R,
285 12
286 12
305 13 W305S, W305L, W305C, W305C, W305R, W305R
308 13 V308F,
301 13
307 13 V307L, V307L,
318 14
302 14 A302V, A302E, A302T,
300 14 A300T, A300S,
306 14 G306V, G306R, G306R,
288 14
303 14 L303P,
326 14
334 14 V334A,
275 14 F275del,
289 14
317 14 D317N, D317G, D317Y,
272 15 G272D, G272S, G272V,
335 15 F335L, F335L, F335L,
296 15 F296S, F296L, F296L, F296L,