SCN5A Variant S354R

Summary of observed carriers, functional annotations, and structural context for SCN5A S354R. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

12%

0/10 effective observations

Estimated BrS1 penetrance

49%

4/10 effective observations

Total carriers

0

0 BrS1 · 0 LQT3 · 0 unaffected

S354R has not been reported in gnomAD. This residue resides in a Hotspot region for Brugada syndrome and a Mild_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 4 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
NA NA NA 0.926 72 12

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
Literature, cohort, and gnomAD 0 0 0 0
Variant features alone 15 11 0 4

Totals may differ from individual publications due to duplicate patients removed during curation.

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near S354R.
Neighbour residue Distance (Å) Observed variants
364 8
277 7
271 12 L271V,
266 13 L266H,
276 6 L276Q, L276P,
363 9
348 7 P348A,
270 12 Q270K,
360 7
279 13
385 13 A385T,
355 5 F355I, F355C,
1549 11
278 11 H278D, H278R,
356 5 D356N,
361 7
904 11 W904X,
366 14
343 12
365 11
376 12 R376H, R376C,
384 12 S384T,
354 0
1546 15 M1546T,
378 15
349 10 D349N,
373 15
267 13
379 15
1550 10
357 7
272 8
274 7 G274C,
362 12
273 9
325 12 L325R,
900 13
392 13
269 9
389 15 Y389H, Y389X,
345 11
393 14
275 9 N275K, N275K,
264 15
912 14 Q912R,
323 14
347 6
382 14
1548 14 G1548K, E1548K,
351 7 G351C, G351D, G351V, G351S,
265 11 A265V,
350 11 H350Q, H350Q,
358 11
903 14 p.M903CfsX29,
367 11 R367C, R367L, R367H,
1551 14 D1551Y, D1551N,
346 10 E346X, E346D, E346D, E346G, E346K,
359 9 A359T, p.A359PfsX12,
344 12 A344S,
381 10 c.1141-3C>A, c.1140+1G>A,
322 15
352 8 Y352C,
368 13
380 10
268 9 G268S,
377 9
353 4 T353I,
907 14