SCN5A Variant M1546T

Summary of observed carriers, functional annotations, and structural context for SCN5A M1546T. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

8%

0/11 effective observations

Estimated BrS1 penetrance

13%

1/11 effective observations

Total carriers

1

0 BrS1 · 0 LQT3 · 1 unaffected

M1546T is present in 1 alleles in gnomAD. This residue resides in a Mild_Hotspot region for Brugada syndrome and a Non_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 1 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-5.53 0.973 -0.87 0.872 12 7

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
Literature, cohort, and gnomAD 1 1 0 0
Variant features alone 15 14 0 1

Totals may differ from individual publications due to duplicate patients removed during curation.

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near M1546T.
Neighbour residue Distance (Å) Observed variants
364 15
271 13 L271V,
266 5 L266H,
363 15
1544 7 T1544P,
270 9 Q270K,
360 13
1627 10
1567 14 F1567L, F1567L, F1567L,
1624 14 V1624I,
1536 14
1552 14 Q1552R, Q1552L,
355 12 F355I, F355C,
1549 10
1538 12
1556 13
356 12 D356N,
1543 5 V1543L, V1543L, V1543A,
1542 6
361 10
260 13
365 13
1564 13
258 12 V258A,
354 15
1546 0 M1546T,
1545 6
1630 12 I1630V, I1630R
1626 12 R1626C, R1626H, R1626P, R1626L,
267 10
1550 14
1560 11 L1560F, L1560F,
262 7 S262G,
357 9
272 15
362 10
261 12
273 12
1559 15 I1559V,
1628 14
1539 10 C1539Y, C1539F,
269 8
1537 14
264 12
259 12
1548 7 E1548K, G1548K,
265 8 A265V,
358 5
263 9 V263I,
359 10 A359T, p.A359PfsX12,
1547 6 V1547L, V1547L,
1563 13
1541 9
1540 10
268 10 G268S,
1623 12 c.4867delC, R1623X, R1623Q, R1623L,