SCN5A Variant L839P

Summary of observed carriers, functional annotations, and structural context for SCN5A L839P. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

7%

0/15 effective observations

Estimated BrS1 penetrance

56%

8/15 effective observations

Total carriers

5

4 BrS1 · 0 LQT3 · 1 unaffected

L839P has not been reported in gnomAD. This residue resides in a Hotspot region for Brugada syndrome and a Mild_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 4 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-6.93 0.999 -3.25 0.989 57 13

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
16426410 2006 5 0 4 0
16643399 2006 1 0 1 0
17404158 2007 1 0 1 0
20031634 2009 5 0 4 0
26921764 2016 1 0 1 0
20129283 2010 1 0 1 0
30059973 2018 1 1 0 0
Literature, cohort, and gnomAD 5 1 0 4
Variant features alone 15 11 0 4

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
16426410 2006
16643399 2006
17404158 2007
20031634 2009
26921764 2016
20129283 2010
30059973 2018
32533946 2020 HEK 3

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near L839P.
Neighbour residue Distance (Å) Observed variants
848 14 I848F,
939 13 L939F,
937 7
839 0 L839P,
842 5
1457 13
240 14 V240M,
1455 10
1452 14
1461 13 T1461S, T1461S,
836 6 V836M,
234 11 P234S,
1451 15 V1451L, V1451D,
934 7
1458 14 S1458Y,
933 10
935 12 L935P,
1464 13 c.4389_4396delCCTCTTTA, L1464P
845 10 c.2533delG,
830 14
833 9 G833R, G833R,
940 11 S940N,
849 15
831 11
420 14
938 9
235 12 c.703+1G>A, G235R, G235R, c.704-1G>C,
840 4
942 11
843 6 T843A,
1456 10
930 11 c.2787+17_2787+18insACACACACACACACACACACACA, c.2788-6C>T,
1459 11 c.4376_4379delTCTT,
834 10 N834D,
1460 9 F1460L, F1460L, F1460L,
837 6
239 10 I239V, I239V ,
1454 14
230 14 I230V, I230T, I230M,
242 15 A242D,
416 12 Y416C,
841 7 p.N841TfsX2, N841K, N841K,
236 13
847 12
941 10 S941N, S941F,
846 10 L846R,
936 11
238 12
233 11
838 5
844 9 L844RfsX3,
829 13
243 15
932 14
832 8
835 5 S835A, S835L,
828 13 L828V,
931 12
1463 13 N1463Y,