SCN5A Variant R893C

Summary of observed carriers, functional annotations, and structural context for SCN5A R893C. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

2%

0/16 effective observations

Estimated BrS1 penetrance

42%

6/16 effective observations

Total carriers

6

3 BrS1 · 0 LQT3 · 3 unaffected

R893C is present in 3 alleles in gnomAD. This residue resides in a Hotspot region for Brugada syndrome and a Non_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 3 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-7.69 1 -5.8 0.967 49 1

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
28341781 2017 1 0 1 0
20129283 2010 2 0 2 0
29574140 2018 1 0 1 0
30059973 2018 1 1 0 0
30371189 2018 1 0 1 0
Literature, cohort, and gnomAD 6 3 0 3
Variant features alone 15 12 0 3

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
28341781 2017
20129283 2010
29574140 2018
30059973 2018
30371189 2018

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near R893C.
Neighbour residue Distance (Å) Observed variants
891 8 I891N, I891T,
880 12
888 10
890 6 I890T,
901 7 E901K, S901L,
919 10
896 7 C896S, C896S,
895 8 L895F,
1417 13
1426 13
894 5 I894M,
1447 13
372 9
926 13
1429 15
371 14 Q371E,
1711 15 c.5131delG
1450 13
904 13 W904X,
887 11
1451 13 V1451L, V1451D,
886 11 H886P, H886Q, H886Q,
1458 14 S1458Y,
376 15 R376C, R376H,
897 6 G897R, G897R, G897E,
1423 11 D1423H,
927 12 N927S, N927K, N927K,
854 13 c.2559delT,
1422 6 M1422R,
857 15 G857D,
1418 8
902 7
892 7 F892I,
373 10
881 12
898 4
893 0 R893C, R893H,
922 11 V922I,
920 14
889 7
1420 10 G1420R, G1420D, G1420V, G1420P,
900 9
1459 14 c.4376_4379delTCTT,
918 14
1425 10
1454 12
1424 13 I1424V,
906 13
878 10 R878C, R878H, R878L,
1421 7
885 15
903 11 p.M903CfsX29,
367 13 R367C, R367H, R367L,
1416 13 c.4245+1G>A, c.4245+1G>C, c.4245+2T>A, A1416E, A1416G,
853 13
370 13 T370M,
877 12
879 7 W879R, W879R,
923 10
905 11
375 15
915 14 C915R,
899 8
1710 15 S1710L,
1415 11
850 13 V850M, c.2549_2550insTG,
1419 10 K1419E,
1414 14 Q1414H, Q1414H,
931 14