SCN5A Variant S910L

Summary of observed carriers, functional annotations, and structural context for SCN5A S910L. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

5%

0/15 effective observations

Estimated BrS1 penetrance

56%

8/15 effective observations

Total carriers

5

4 BrS1 · 0 LQT3 · 1 unaffected

S910L is present in 1 alleles in gnomAD. This residue resides in a Mild_Hotspot region for Brugada syndrome and a Mild_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 4 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-2.62 0.982 -2.34 0.808 58 14

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
24768612 2014 3 0 3 0
11901046 2002 1 0 1 0
28104484 2017 1 0 0 1 SSS
20129283 2010 1 0 1 0
29325976 2018 2 0 2 0
29574140 2018 1 0 1 0
Literature, cohort, and gnomAD 5 1 0 4
Variant features alone 15 11 0 4

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
24768612 2014 HEK 0
11901046 2002
28104484 2017
20129283 2010
29325976 2018
29574140 2018

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near S910L.
Neighbour residue Distance (Å) Observed variants
880 14
856 14 V856L, V856L,
890 15 I890T,
901 15 E901K, S901L,
919 12
870 13
862 9
867 10 E867K, E867Q, E867X,
859 13
360 15
863 9
904 12 W904X,
864 6
216 13 S216X, S216L,
871 12
909 4
876 14
857 11 G857D,
868 9 c.2602delC, L868X,
902 12
882 14
881 10
860 9 p.L860fsx89,
911 4 G911E,
900 15
858 14 M858L, M858L,
217 15
918 12
917 12 L917V, L917R
865 8
913 6
916 11
912 7 Q912R,
906 5
866 11 S866P, S866L,
351 15 G351S, G351C, G351D, G351V,
910 0 S910L,
350 13 H350Q, H350Q,
903 10 p.M903CfsX29,
877 14
869 13 R869S, R869S,
905 9
352 12 Y352C,
915 7 C915R,
215 14 p.L215CfsX10,
908 7
914 7
861 6 p.F861WfsX90, c.2582_2583delTT,
220 14 T220I,
907 7