SCN5A Variant A1427S

Summary of observed carriers, functional annotations, and structural context for SCN5A A1427S. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

3%

0/11 effective observations

Estimated BrS1 penetrance

44%

4/11 effective observations

Total carriers

1

1 BrS1 · 0 LQT3 · 0 unaffected

A1427S has not been reported in gnomAD. This residue resides in a Hotspot region for Brugada syndrome and a Non_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 3 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-2.85 0.943 0.31 0.892 52 1

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
20129283 2010 1 0 1 0
Literature, cohort, and gnomAD 1 0 0 1
Variant features alone 15 12 0 3

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
24445991 2014 HEK 16 2.5 0
20129283 2010

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near A1427S.
Neighbour residue Distance (Å) Observed variants
1355 12
1403 13
1357 12 A1357V,
1430 5 D1430N,
1352 13
1426 5
1445 14 Y1445H,
1361 9
1447 13
1444 11 L1444I,
1440 10 W1440X,
1382 15 S1382I,
1395 14
1397 11 c.4189delT, c.4190delA,
1449 13 Y1449S, Y1449C,
1380 12 p.N1380del, N1380K, N1380K,
1429 6
1442 12 Y1442N, Y1442C,
1450 11
1398 8 V1398M,
1411 12
1353 15 V1353M,
1407 14
886 14 H886P, H886Q, H886Q,
1714 14 D1714G
1358 11 G1358R, G1358R, G1358W,
1396 12
1362 7 c.4083delG, R1362S, R1362S,
1433 11 G1433R, G1433R, G1433W, G1433V,
1438 8 P1438L,
1423 7 D1423H,
1437 11
1431 6 S1431C,
1422 10 M1422R,
1359 8 K1359M, K1359N, K1359N,
1356 8 c.4066_4068delTT,
1434 13 c.4299_4300insG, c.4299+1delG, c.4299+1G>T, c.4299+28C>T, c.4299+2T>A, c.4299delG, c.4299G>A, Y1434X, c.4300-1G>A, c.4300-2A>T,
1412 14 L1412F,
1408 13 G1408R, G1408R,
889 14
1420 11 G1420R, G1420D, G1420V, G1420P,
1360 5 F1360C,
1401 10
1425 7
1399 12
1427 0 A1427S, A1427E,
1446 12
1424 6 I1424V,
1432 11 R1432G, R1432S, R1432S,
1439 10 Q1439R, Q1439H, Q1439H,
1364 13 I1364V,
878 10 R878C, R878H, R878L,
1400 9 V1400I,
1421 12
1443 11 N1443S,
1441 12 E1441Q,
879 12 W879R, W879R,
1415 13
1428 4 A1428S, A1428V,
1363 13 C1363Y,
1436 14
1414 14 Q1414H, Q1414H,
1402 10