SCN5A Variant V1604M

Summary of observed carriers, functional annotations, and structural context for SCN5A V1604M. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

2%

0/19 effective observations

Estimated BrS1 penetrance

22%

4/19 effective observations

Total carriers

9

1 BrS1 · 0 LQT3 · 8 unaffected

V1604M is present in 8 alleles in gnomAD. This residue resides in a Hotspot region for Brugada syndrome and a Non_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 3 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-2.21 0.844 3.15 0.833 46 1

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
20129283 2010 1 0 1 0
Literature, cohort, and gnomAD 9 8 0 1
Variant features alone 15 12 0 3

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
20129283 2010

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near V1604M.
Neighbour residue Distance (Å) Observed variants
1600 7
1571 15 F1571C,
1606 7 T1606I,
1610 8 D1610G,
1569 14 A1569P,
1612 13
1615 13 Y1615X,
1572 13
1564 14
1596 12 F1596I, F1596C,
1605 4 c.4813+2_4813+5dupTGGG, c.4813+3_4813+6dupGGGT, c.4813+5insTGGG, G1605C, G1605D,
1611 11 I1611V,
1597 10 V1597M,
1616 7
1607 7
1599 9
1620 14 T1620K, T1620M,
1568 12
1617 6 p.F1617del,
1608 5
1565 13 L1565M,
1604 0 c.4810+3_4810+6dupGGGT, V1604M,
1602 6
1622 9
1618 10
1614 13
1626 13 R1626C, R1626H, R1626P, R1626L
1601 5 L1601H,
1621 12
1609 8 S1609W, S1609L,
1603 5 I1603F,
1598 10 V1598A,
1623 14 c.4867delC, R1623X, R1623Q, R1623L,
1619 11 P1619Q, P1619L, c.4856delC,
1625 13
1613 10 Q1613L, Q1613H, Q1613H,