SCN5A Variant G1631D

Summary of observed carriers, functional annotations, and structural context for SCN5A G1631D. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

51%

3/12 effective observations

Estimated BrS1 penetrance

19%

2/12 effective observations

Total carriers

2

0 BrS1 · 2 LQT3 · 0 unaffected

G1631D has not been reported in gnomAD. This residue resides in a Mild_Hotspot region for Brugada syndrome and a Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 2 individuals for Brugada syndrome and 1 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-6.47 0.954 -4.02 0.982 29 40

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
19808432 2008 2 2 0 0
27566755 2016 2 2 0 0
30059973 2018 1 1 0 0
Literature, cohort, and gnomAD 2 0 2 0
Variant features alone 15 12 1 2

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
19808432 2008 tsA201 100 12 14 543
29017927 2017
27566755 2016
30059973 2018

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near G1631D.
Neighbour residue Distance (Å) Observed variants
266 14 L266H,
1643 14 I1643L,
1627 9
1624 13 V1624I,
1536 14
1538 9
1531 13
1635 7
1634 5 L1634P,
1534 13
1542 11
1650 14 L1650F
260 10
1571 15 F1571C,
258 14 V258A,
1654 15
1630 4 I1630V, I1630R,
1532 14 V1532I, V1532F,
1626 13 R1626C, R1626H, R1626P, R1626L,
267 14
1644 13 R1644C, R1644H, R1644L,
1625 12
262 12 S262G,
256 11
399 13
261 14
1628 6
1589 12
1632 5 R1632C, R1632H, R1632L,
1597 15 V1597M,
1539 10 C1539Y, C1539F,
255 14
395 14
1535 9
1537 14
1594 10 F1594S,
264 12
1638 14 R1638X, R1638Q,
1651 12
259 8
1633 5
1591 6 W1591X,
1593 13 I1593M,
1595 10
1637 10
1636 9
263 9 V263I,
1629 8 R1629G, R1629X, R1629Q,
1574 15 c.4719C>T, E1574K,
1541 13
1592 11
1540 15
1631 0 G1631D,
1590 10
1647 11
257 14
400 15 G400R, G400R, G400E, G400A,
1598 14 V1598A,