SCN5A Variant S1672Y

Summary of observed carriers, functional annotations, and structural context for SCN5A S1672Y. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

4%

0/13 effective observations

Estimated BrS1 penetrance

64%

8/13 effective observations

Total carriers

3

3 BrS1 · 0 LQT3 · 0 unaffected

S1672Y has not been reported in gnomAD. This residue resides in a Hotspot region for Brugada syndrome and a Non_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 5 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-4.16 0.996 -5.06 0.951 75 1

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
16643399 2006 1 0 1 0
17404158 2007 3 0 3 0
26921764 2016 3 0 3 0
20129283 2010 1 0 1 0
20129283 2010 1 0 1 0
30059973 2018 1 1 0 0
Literature, cohort, and gnomAD 3 0 0 3
Variant features alone 15 10 0 5

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
16643399 2006
17404158 2007
26921764 2016
20129283 2010
20129283 2010
30059973 2018
32533946 2020 HEK 1

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near S1672Y.
Neighbour residue Distance (Å) Observed variants
1702 11
387 15
1218 15 S1218T, S1218I,
1304 10 T1304M,
1698 9 A1698T,
1220 12 G1220E,
1673 4
1675 6
1754 13
1707 11
1694 7
1704 7 L1704H,
1226 9
1706 13 Q1706H, Q1706H,
1747 14 V1747M,
1695 11 Q1695X,
1716 14 p.L1716SfsX71,
1669 6
1671 7
1221 13 A1221V,
1668 7 M1668T,
1676 5 M1676T, M1676I, M1676I, M1676I,
1692 14
1219 11 S1219N,
1672 0 S1672Y,
1693 11
1699 10
1310 14
1306 15 R1306S, R1306H,
1665 10
1305 13
1680 12 A1680T, A1680P,
1703 9
1663 14
1759 14 S1759C
1701 7 M1701I, M1701I, M1701I,
1307 10
1758 14 I1758V, p.I1758del,
1228 14 Y1228H, Y1228C, Y1228F,
1678 10 N1678S,
1223 8 c.3667delG,
1755 10
1697 8
1222 10 p.L1222LfsX7, L1222R,
1227 12
1674 7 F1674V,
390 14
1748 14 p.G1748del, G1748D,
1708 12 T1708I,
1301 12
1696 9
1705 11
1700 5
1751 9
1311 15 L1311P,
1677 9
1682 14
1308 12 L1308F,
1752 12
1224 11
1670 6
1225 11 E1225K, G1225K,
1720 14 c.5157delC,
1679 9
1667 9 V1667I,
1664 13
1303 14 R1303W, R1303Q,
1666 10