SCN5A Variant N1722D

Summary of observed carriers, functional annotations, and structural context for SCN5A N1722D. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

5%

0/18 effective observations

Estimated BrS1 penetrance

33%

5/18 effective observations

Total carriers

8

3 BrS1 · 0 LQT3 · 5 unaffected

N1722D has not been reported in gnomAD. This residue resides in a Mild_Hotspot region for Brugada syndrome and a Non_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 2 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-4.46 0.986 1.75 0.741 37 8

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
20031634 2009 8 0 3 0
20129283 2010 1 0 1 0
30059973 2018 2 2 0 0
Literature, cohort, and gnomAD 8 5 0 3
Variant features alone 15 13 0 2

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
20031634 2009
20129283 2010
30059973 2018
32533946 2020 HEK 37 6.9 6

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near N1722D.
Neighbour residue Distance (Å) Observed variants
1746 9 A1746T, A1746V,
1724 6
1741 12 D1741N, D1741Y, D1741E, D1741E,
1406 14 G1406R, G1406R, G1406E,
1715 14
1726 11
1745 5
1397 13 c.4189delT, c.4190delA,
1743 6 G1743R, G1743R, G1743E,
1723 5 T1723N,
1725 7 P1725L,
1398 14 V1398M,
1407 13
1410 13
1747 10 V1747M,
1716 14 p.L1716SfsX71,
1714 14 D1714G,
1404 15
1744 6 S1744I,
1721 5
1742 8
1680 14 A1680T, A1680P,
1727 12
1719 9
1731 11
1728 8 C1728R, C1728Y, C1728W,
1678 14 N1678S,
1401 13
1399 9
1748 10 p.G1748del, G1748D,
1730 13 P1730A, P1730H, P1730L,
1683 11
1400 13 V1400I,
1718 9 S1718R, S1718R, S1718R,
1717 10 L1717P,
1751 15
1682 11
1750 13 L1750F
1752 14
1722 0 N1722D,
1686 14
1749 10 I1749N,
1729 12 D1729N,
1740 13 G1740R, G1740R,
1720 8 c.5157delC,
1732 13
1679 12
1685 12