SCN5A Variant c.5356_5357delCT

Summary of observed carriers, functional annotations, and structural context for SCN5A c.5356_5357delCT. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

18%

1/15 effective observations

Estimated BrS1 penetrance

49%

7/15 effective observations

Total carriers

5

5 BrS1 · 0 LQT3 · 0 unaffected

c.5356_5357delCT has not been reported in gnomAD. This residue resides in a Mild_Hotspot region for Brugada syndrome and a Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 2 individuals for Brugada syndrome and 1 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
NA NA NA None 27 48

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
16643399 2006 1 0 1 0
28781330 2017 3 0 3 0
20129283 2010 2 0 2 0
Literature, cohort, and gnomAD 5 0 0 5
Variant features alone 15 12 1 2

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
16643399 2006
28781330 2017
20129283 2010

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near c.5356_5357delCT.
Neighbour residue Distance (Å) Observed variants
1855 12
1785 5
1794 11
1856 12
1778 10
1853 14 I1853V,
1795 13 Y1795N, Y1795H, p.Y1795_E1796insD, Y1795C,
1652 15 M1652T, M1652R,
1777 12 V1777M, V1777L, V1777L,
1866 13
1824 7 P1824A,
1492 13
1504 12 K1504E,
1641 12
1491 14 Q1491H, Q1491H,
1863 12
1851 15 M1851V, M1851I, M1851I, M1851I,
1501 9 p.L1501_K1505del, L1501V,
1860 12 c.5577_5578dupAA,
1857 11
1862 8
1779 12 T1779M,
1493 9 p.K1493del, K1493X, K1493R,
1858 7
1865 11
1787 4 S1787N,
1786 0 c.5356_5357delCT, L1786Q, L1786R,
1648 12
1861 7 V1861I, V1861F
1495 13 Y1495S,
1649 15 A1649V,
1864 12
1821 12
1644 14 R1644C, R1644H, R1644L,
1826 13 R1826C, R1826H,
1496 10
1854 10
1825 8 L1825P,
1797 15 I1797V,
1793 11 M1793K,
1781 7 E1781G, E1781D, E1781D,
1789 9
1499 13
1645 12 T1645M,
1784 8 E1784K, E1784X,
1827 15
1498 11 M1498V, M1498T, M1498R,
1796 15
1780 12 E1780G,
1788 8 c.5361_5364delTGAG,
1500 7 p.K1500del,
1859 12
1791 6
1792 10 D1792N, D1792Y, D1792V,
1823 11 E1823K, p.E1823HfsX10,
1502 13 G1502S, G1502A,
1783 9
1497 7
1490 14
1790 5 D1790N, D1790G, p.D1790del,
1494 11
1503 13 S1503Y,
1822 10 c.5464_5467delTCTG, c.5464-5467delTCTG,
1782 8