KCNQ1 Variant A341E

Summary of observed carriers, functional annotations, and structural context for KCNQ1 A341E. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT1 penetrance

77%

10/14 effective observations

Total carriers

4

3 LQT1 · unaffected

Functional studies

1

Publications with functional data

A341E has not been reported in gnomAD. This residue resides in a Hotspot region for LQT1.

Variant features alone are equivalent to phenotyping 7 individuals with LQT1 and 3 unaffected individuals.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density LQT1 (%)
-4.68 1.0 -3 0.95 85

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. BLAST-PSSM reflects evolutionary conservation; more negative values indicate rarer substitutions. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT1 Other Disease
34135346 2021 1 1 None None
32893267 2020 1 None 1 None
30758498 2019 1 None None None
24217263 2013 1 None 1 None
23631430 2013 2 None None None
23153844 2012 11 None 1 None
22949429 2012 1 None 1 None
22677073 2012 1 None None SUDS
19841300 2009 1 None 1 None
19716085 2009 4 None 4 None
19490272 2009 10 None 10 None
17470695 2007 9 None 9 None
14678125 2003 7 None 7 None
Literature, cohort, and gnomAD 4 3
Variant features alone 15 3 7

Totals may differ from individual publications due to duplicate patients removed during curation.