KCNQ1 Variant G350V

Summary of observed carriers, functional annotations, and structural context for KCNQ1 G350V. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT1 penetrance

80%

10/13 effective observations

Total carriers

3

3 LQT1 · 0 unaffected

Functional studies

0

Publications with functional data

G350V has not been reported in gnomAD. This residue resides in a Hotspot region for LQT1.

Variant features alone are equivalent to phenotyping 7 individuals with LQT1 and 3 unaffected individuals.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density LQT1 (%)
-8.26 1.0 -2 0.921 84

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. BLAST-PSSM reflects evolutionary conservation; more negative values indicate rarer substitutions. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT1 Other Disease
32893267 2020 3 None 3 None
23631430 2013 1 None None None
Literature, cohort, and gnomAD 3 0 3
Variant features alone 15 3 7

Totals may differ from individual publications due to duplicate patients removed during curation.

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near G350V.
Neighbour residue Distance (Å) Observed variants
349 9 S349W,
352 10
353 11 L353P,
348 11
350 11 G350V, G350R, G350R, G350W,
345 12 G345R, G345R, G345A,
358 13 K358T,
346 13
356 13
351 13 F351L, F351L, F351L, F351S,
260 13
355 14
347 14 L347P, L347R,
256 14
344 14 A344V, A344E,
259 14 R259C, R259H, R259L, R259G
257 15 I257V,