KCNQ1 Variant G460C

Summary of observed carriers, functional annotations, and structural context for KCNQ1 G460C. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT1 penetrance

10%

1/11 effective observations

Total carriers

1

0 LQT1 · 1 unaffected

Functional studies

0

Publications with functional data

G460C is present in 1 alleles in gnomAD. This residue resides in a Non_Hotspot region for LQT1.

Variant features alone are equivalent to phenotyping 1 individuals with LQT1 and 9 unaffected individuals.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density LQT1 (%)
-1.86 0.997 -3 0.559 4

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. BLAST-PSSM reflects evolutionary conservation; more negative values indicate rarer substitutions. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT1 Other Disease
Literature, cohort, and gnomAD 1 1 0
Variant features alone 15 9 1

Totals may differ from individual publications due to duplicate patients removed during curation.

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near G460C.
Neighbour residue Distance (Å) Observed variants
460 0 G460S, G460D, G460C,
459 4 D459N, D459V,
461 4
458 5
462 5 D462N
457 7
463 7 S463T,
456 8 F456L, F456L, F456L,
464 8 S464P,
455 8 H455Y, H455Q, H455Q, H455R,
465 8
454 9
466 9
453 10
467 10 K467R,
452 11 R452Q, R452W, R452L,
468 11 S468G, S468N,
451 11 R451Q, R451W,
469 11
450 12 E450K,
470 12
449 13 E449K,
471 13
448 13 P448R, P448Q, P448L, P448S,
472 13 L472P,
447 14 P447H,
473 14 E473Q,
446 14 D446E, D446E, D446E, D446E, D446N,
474 14
445 15
475 15