KCNQ1 Variant P570L

Summary of observed carriers, functional annotations, and structural context for KCNQ1 P570L. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT1 penetrance

78%

10/14 effective observations

Total carriers

4

4 LQT1 · 0 unaffected

Functional studies

0

Publications with functional data

P570L has not been reported in gnomAD. This residue resides in a Hotspot region for LQT1.

Variant features alone are equivalent to phenotyping 6 individuals with LQT1 and 4 unaffected individuals.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density LQT1 (%)
-6.76 0.049 -4 0.697 82

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. BLAST-PSSM reflects evolutionary conservation; more negative values indicate rarer substitutions. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT1 Other Disease
32893267 2020 4 None 4 None
Literature, cohort, and gnomAD 4 0 4
Variant features alone 15 4 6

Totals may differ from individual publications due to duplicate patients removed during curation.

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near P570L.
Neighbour residue Distance (Å) Observed variants
570 0 P570L,
569 4 K569E,
571 4 S571L, S571P,
568 5 G568R, G568R, G568E,
572 5
567 7 I567T, I567S,
573 7 F573L, F573L, F573L,
566 8 S566F, S566Y, S566P,
574 8 I574V,
565 8
575 8
564 9 D564H, D564N,
576 9 V576I,
563 10
577 10
562 11 R562M, R562S, R562S,
578 11 E578K, E578V,
561 11
579 11
560 12
580 12 S580G, S580N,
559 13 L559P,
581 13
558 13
582 13
557 14 K557E,
583 14 R583H, R583C, R583G,
556 14
584 14 G584S,
555 15 R555H, R555C, R555S, R555L,
585 15 S585N