SCN5A Variant c.3940_3941delCT

Summary of observed carriers, functional annotations, and structural context for SCN5A c.3940_3941delCT. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

3%

0/11 effective observations

Estimated BrS1 penetrance

52%

5/11 effective observations

Total carriers

1

1 BrS1 · 0 LQT3 · 0 unaffected

c.3940_3941delCT has not been reported in gnomAD. This residue resides in a Hotspot region for Brugada syndrome and a Non_Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 4 individuals for Brugada syndrome and 0 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
NA NA NA None 69 1

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
19026623 2009 1 0 1 0
24687331 2014 1 1 0 0
Literature, cohort, and gnomAD 1 0 0 1
Variant features alone 15 11 0 4

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
19026623 2009
24687331 2014

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near c.3940_3941delCT.
Neighbour residue Distance (Å) Observed variants
1328 13 V1328M,
1659 8
1271 11 W1271C, W1271C,
1315 5
1274 14
1216 11 L1216V,
1314 0 c.3940_3941delCT,
1320 5 M1320I, M1320I, M1320I,
1213 15
1666 7
1656 12
1309 12 R1309C, R1309H,
1669 12
1668 14 M1668T,
1219 14 S1219N,
1660 10 I1660V, I1660S,
1313 5
1310 7
1316 8 R1316Q, R1316L,
1766 14 M1766L, M1766V, M1766L, M1766T
1319 9 G1319V,
1665 10
1663 7
1657 14
1662 6
1324 8
1317 6 F1317C,
1327 12
1307 12
1318 10
1321 9 R1321K,
1323 9 V1323G,
1215 12 I1215V,
1212 10 p.I1212del,
1322 11 c.3963+2T>C, c.3963+4A>G,
1211 14
1312 7
1326 13 A1326S,
1763 13 V1763M, V1763L, V1763L,
1311 6 L1311P,
1308 11 L1308F,
1670 12
1661 10 G1661R, G1661R, G1661E,
1209 13 T1209R,
1655 13
1325 12 N1325S,
1208 14 E1208K, E1208X,
1667 11 V1667I,
1664 11
1658 13