SCN5A Variant I1334V

Summary of observed carriers, functional annotations, and structural context for SCN5A I1334V. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

51%

4/13 effective observations

Estimated BrS1 penetrance

9%

1/13 effective observations

Total carriers

3

0 BrS1 · 2 LQT3 · 1 unaffected

I1334V is present in 1 alleles in gnomAD. This residue resides in a Mild_Hotspot region for Brugada syndrome and a Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 1 individuals for Brugada syndrome and 2 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-0.98 0.995 2.6 0.881 13 56

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
22677073 2012 1 0 0 1 SUDS
23098067 2012 1 1 0 0
19716085 2009 1 1 0 0
30059973 2018 3 3 0 0
Literature, cohort, and gnomAD 3 1 2 0
Variant features alone 15 12 2 1

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
22677073 2012
23098067 2012
19716085 2009
30059973 2018

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near I1334V.
Neighbour residue Distance (Å) Observed variants
1328 10 V1328M,
1765 11
1340 10 V1340I,
1757 8
1472 10 p.N1472del, N1472S,
1339 10 L1339F, p.L1339del,
1756 13 I1756V,
1461 12 T1461S, T1461S,
1764 14 c.5290delG, V1764F,
1333 4
1754 13
1471 12
1762 7 p.I1762del, I1762M,
1470 13
1464 10 c.4389_4396delCCTCTTTA, L1464P,
1466 11 c.4396_4397insG,
1753 14 T1753A,
944 14
1329 8 G1329S,
1769 15
1766 11 M1766L, M1766V, M1766L, M1766T
1334 0 I1334V,
1473 13 F1473S, F1473C,
1341 10
1468 7 V1468F, V1468A,
1462 12
1759 13 S1759C,
1324 14
1327 9
942 14
1758 10 I1758V, p.I1758del,
1330 5 A1330T, A1330P, A1330D,
1460 14 F1460L, F1460L, F1460L,
1323 15 V1323G,
1338 6 L1338V,
1343 15
1345 14 W1345C, W1345C,
1337 5
1342 13
1326 11 A1326S,
1763 12 V1763M, V1763L, V1763L,
1332 6 P1332Q, P1332L,
1465 6 p.F1465_L1480dup,
1760 13
1467 10
1331 5 I1331V,
1761 9 c.5280delG, L1761F, L1761H,
1469 8 I1469V,
1336 7
824 13
1325 14 N1325S,
1335 5 M1335R,
828 14 L828V,
1463 13 N1463Y,