SCN5A Variant G1329S

Summary of observed carriers, functional annotations, and structural context for SCN5A G1329S. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

44%

5/17 effective observations

Estimated BrS1 penetrance

9%

1/17 effective observations

Total carriers

7

0 BrS1 · 3 LQT3 · 4 unaffected

G1329S is present in 2 alleles in gnomAD. This residue resides in a Mild_Hotspot region for Brugada syndrome and a Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 1 individuals for Brugada syndrome and 2 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-5.84 1 1.66 0.878 13 55

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
21216356 2011 1 1 0 0
24667783 2015 4 2 0 0
Literature, cohort, and gnomAD 7 4 3 0
Variant features alone 15 12 2 1

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
21216356 2011
24667783 2015

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near G1329S.
Neighbour residue Distance (Å) Observed variants
1328 4 V1328M,
1271 14 W1271C, W1271C,
1480 15 c.4437+5G>A, c.4438-1C>T,
1765 14
1757 14
1472 7 p.N1472del, N1472S,
1315 14
1320 14 M1320I, M1320I, M1320I,
1333 7
1270 14 A1270S,
1477 14 K1477N, K1477N,
1471 11
1762 11 p.I1762del, I1762M,
1470 13
1466 14 c.4396_4397insG,
1478 15 K1478E,
944 14
1329 0 G1329S,
1769 14
1766 11 M1766L, M1766V, M1766L, M1766T
1479 11
1473 10 F1473S, F1473C,
1334 8 I1334V,
1468 10 V1468F, V1468A,
1474 13
1324 9
1327 6
1758 13 I1758V, p.I1758del,
1330 3 A1330T, A1330P, A1330D,
1321 15 R1321K,
1323 10 V1323G,
1338 14 L1338V,
1322 11 c.3963+2T>C, c.3963+4A>G,
1337 13
1326 5 A1326S,
1763 13 V1763M, V1763L, V1763L,
1332 5 P1332Q, P1332L,
1465 13 p.F1465_L1480dup,
1467 13
1476 9 Q1476X, Q1476R,
1331 5 I1331V,
1761 15 c.5280delG, L1761F, L1761H,
1475 11 p.Q1475NfsX6, Q1475L,
1469 9 I1469V,
1336 12
1325 7 N1325S,
1335 10 M1335R,