SCN5A Variant Y1767C

Summary of observed carriers, functional annotations, and structural context for SCN5A Y1767C. Data combine curated literature, international cohorts, and gnomAD observations.

Estimated LQT3 penetrance

84%

10/18 effective observations

Estimated BrS1 penetrance

7%

1/18 effective observations

Total carriers

8

0 BrS1 · 8 LQT3 · 0 unaffected

Y1767C has not been reported in gnomAD. This residue resides in a Non_Hotspot region for Brugada syndrome and a Hotspot region for LQT3.

Variant features alone are equivalent to phenotyping 1 individuals for Brugada syndrome and 2 individuals for LQT3.

In silico predictors

Variant-level computational predictors.
PROVEAN PolyPhen-2 BLAST-PSSM REVEL Penetrance Density BrS (%) Penetrance Density LQT3 (%)
-8.31 0.995 -3.05 0.982 9 73

PROVEAN scores below -2 suggest deleterious impact. REVEL scores above 0.5–0.75 are often interpreted as likely pathogenic. PolyPhen-2 scores above 0.85 are typically pathogenic. Penetrance density summarises neighbouring residue risk (Kroncke et al. 2019).

Reported carrier data

Observed carriers by publication or cohort.
Source Year Carriers Unaffected LQT3 BrS1 Other Other Disease
21076026 2011 4 4 0 0
16414944 2005 1 1 0 0
27566755 2016 4 4 0 0
30059973 2018 2 2 0 0
Literature, cohort, and gnomAD 8 0 8 0
Variant features alone 15 12 2 1

Totals may differ from individual publications due to duplicate patients removed during curation.

Functional data

Peak and late/persistent current values are relative to wild-type (100% indicates no change). V1/2 activation and inactivation denote the membrane potentials (mV) at which half-maximal current is achieved.

Published electrophysiology measurements.
PubMed ID Year Cell Type Peak Current (% WT) V1/2 Activation (mV) V1/2 Inactivation (mV) Late/Persistent Current (% WT)
25028482 2014 HEK 100
21076026 2011 tsA201 100 -3 0 600
16414944 2005
27566755 2016
26150789 2015 HEK 0
30059973 2018

Nearby variants

Neighbouring residues within 15 Ångström provide structural context. Variants listed in the right-most column have been observed clinically or in gnomAD.

Previously observed variants near Y1767C.
Neighbour residue Distance (Å) Observed variants
403 7
1659 10
404 11 L404V, L404Q,
1773 12
1765 8
396 14 V396L, V396A,
1653 8
1771 6 I1771T,
401 9 S401P,
1652 13 M1652T, M1652R,
1320 12 M1320I, M1320I, M1320I,
1764 6 c.5290delG, V1764F,
371 13 Q371E,
409 12 L409V, L409P,
1650 11 L1650F,
1656 8
1477 14 K1477N, K1477N,
1762 11 p.I1762del, I1762M,
1470 12
1668 15 M1668T,
1466 11 c.4396_4397insG,
369 14 M369K,
1767 0 Y1767C,
1660 6 I1660V, I1660S,
1654 10
1769 7
402 5 F402L, F402L, F402L,
1766 7 M1766L, M1766V, M1766L, M1766T,
1319 13 G1319V,
1665 14
1649 13 A1649V,
1768 6 I1768V,
1774 11 N1774D, c.5321_5324dupACTT,
1473 11 F1473S, F1473C,
1663 10
399 10
397 11 I397V, I397F, I397T,
405 10
1657 5
1759 11 S1759C,
1662 11
1324 14
1327 14
1709 12 p.T1709del, T1709R, T1709M,
1758 14 I1758V, p.I1758del,
1772 10 L1772V,
395 14
1323 10 V1323G,
394 13
410 13 A410V,
1770 6 I1770V,
1651 14
1708 12 T1708I,
408 14
1705 15
1322 13 c.3963+2T>C, c.3963+4A>G,
407 12
1326 13 A1326S,
1763 8 V1763M, V1763L, V1763L,
1760 12
1467 15
1775 14 F1775V, p.F1775LfsX15
1661 8 G1661R, G1661R, G1661E,
1761 13 c.5280delG, L1761F, L1761H,
1655 10
1469 11 I1469V,
406 8 N406S, N406K, N406K,
398 7
400 10 G400R, G400R, G400E, G400A,
1667 14 V1667I,
1664 9
1658 9